Please use this identifier to cite or link to this item:
http://hdl.handle.net/10397/106201
DC Field | Value | Language |
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dc.contributor | Department of Rehabilitation Sciences | en_US |
dc.creator | Xu, RH | en_US |
dc.creator | Ma, B | en_US |
dc.creator | Xin, HP | en_US |
dc.creator | Zhang, HY | en_US |
dc.creator | Zeng, Y | en_US |
dc.creator | Luo, N | en_US |
dc.creator | Dong, D | en_US |
dc.date.accessioned | 2024-05-03T00:45:45Z | - |
dc.date.available | 2024-05-03T00:45:45Z | - |
dc.identifier.uri | http://hdl.handle.net/10397/106201 | - |
dc.language.iso | en | en_US |
dc.publisher | BioMed Central | en_US |
dc.rights | © The Author(s) 2023. Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated in a credit line to the data. | en_US |
dc.rights | The following publication Xu, R.H., Ma, B., Xin, H. et al. Measurement properties of the EQ-5D-5L and PROPr in patients with spinal muscular atrophy. Health Qual Life Outcomes 21, 123 (2023) is available at https://dx.doi.org/10.1186/s12955-023-02204-z. | en_US |
dc.subject | EQ-5D | en_US |
dc.subject | PROMIS | en_US |
dc.subject | Health-related quality of life | en_US |
dc.subject | Spinal muscular atrophy | en_US |
dc.title | Measurement properties of the EQ-5D-5L and PROPr in patients with spinal muscular atrophy | en_US |
dc.type | Journal/Magazine Article | en_US |
dc.identifier.volume | 21 | en_US |
dc.identifier.doi | 10.1186/s12955-023-02204-z | en_US |
dcterms.abstract | Objectives Spinal muscular atrophy (SMA) is a rare monogenic neuromuscular disorder caused by loss of function mutations. Measuring health-related quality of life to support economic evaluations in this population is encouraged. However, empirical evidence on the performance of preference-based measures (PBMs) in individuals with SMA is limited. This study aimed to assess the psychometric properties of the EQ-5D-5L and the Patient-Reported Outcomes Measure Information System Preference measure (PROPr) in individuals with SMA. Methods The data used in this study were obtained via a web-based, cross-sectional survey. All participants completed the self-reporting EQ-5D-5L and PROMIS-29 questionnaires. Information about their socioeconomic and health status was also obtained. Ceiling and floor effects, convergent and divergent validity, known-group validity, and the agreement between the two measures were assessed. Results Strong ceiling and floor effects were observed for four dimensions of the EQ-5D-5L and three subscales, including pain intensity, pain interference, and physical function, of the PROMIS-29. All hypothesized associations between EQ-5D-5L/PROMIS-29 and other neuromuscular questions were confirmed, supporting good convergent validity. Moreover, both EQ-5D-5L and PROPr scores differentiated between impaired functional groups, demonstrating good discriminative ability. Poor agreement between the EQ-5D-5L and PROPr utility scores was observed. Conclusions The EQ-5D-5L and PROPr both appear to be valid PBMs for individuals with SMA. However, PROPr yielded considerably lower utility scores than EQ-5D-5L and their agreement was poor. Therefore, these two PBMs may not be used interchangeably in economic evaluations of SMA-related interventions. | en_US |
dcterms.accessRights | open access | en_US |
dcterms.bibliographicCitation | Health and quality of life outcomes, 2023, v. 21, 123 | en_US |
dcterms.isPartOf | Health and quality of life outcomes | en_US |
dcterms.issued | 2023 | - |
dc.identifier.isi | WOS:001105626900001 | - |
dc.identifier.eissn | 1477-7525 | en_US |
dc.identifier.artn | 123 | en_US |
dc.description.validate | 202405 bcrc | en_US |
dc.description.oa | Version of Record | en_US |
dc.identifier.FolderNumber | OA_Scopus/WOS | - |
dc.description.pubStatus | Published | en_US |
dc.description.oaCategory | CC | en_US |
Appears in Collections: | Journal/Magazine Article |
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File | Description | Size | Format | |
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s12955-023-02204-z.pdf | 1.57 MB | Adobe PDF | View/Open |
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